Case ReportCOMPLICATED CONGENITAL RETINOSCHISISSavoie, Brian T. MD*; Ferrone, Philip J. MD*,†Author Information *Department of Ophthalmology, Hofstra Northwell School of Medicine, Great Neck, New York; and †Long Island Vitreoretinal Consultants, Great Neck, New York. Reprint requests: Philip J. Ferrone, MD, Long Island Vitreoretinal Consultants, 600 Northern Boulevard, Suite 216, Great Neck, NY 11021; e-mail: [email protected] Presented by P. J. Ferrone, MD, at the Atlantic Coast Retinal Club and Macula 2016, New York, NY, January 8, 2016. None of the authors have any financial/conflicting interests to disclose. Retinal Cases & Brief Reports: Winter 2017 - Volume 11 - Issue - p S202-S210 doi: 10.1097/ICB.0000000000000444 Buy Metrics AbstractIn Brief Purpose: To describe the treatment and natural history of a patient with complicated congenital retinoschisis. Methods: A retrospective case report. A 10-month-old boy with congenital retinoschisis presented with tractional retinal detachments and foveal schisis in both eyes. Results: On presentation, vision was decreased in both eyes with presumed amblyopia of the left eye. Funduscopic examination revealed bilateral foveal schisis and tractional retinal detachment involving the macula. Follow-up examination revealed superior retinal dragging and peripheral ischemia on fluorescein angiogram in both eyes. Nine months after presentation, combined rhegmatogenous and tractional retinal detachment developed in the right eye and was treated by scleral buckle. After vitrectomy for nonclearing vitreous hemorrhage in the left eye, a combined rhegmatogenous and tractional retinal detachment developed. Vitrectomy and lensectomy with silicone oil was performed. At 6 years of follow-up, both retinas were attached and foveal schisis had resolved. Conclusion: Sight threatening complications of congenital retinoschisis include retinal detachment and vitreous hemorrhage. Vitrectomy and/or scleral buckling may prevent progression of vision loss and promote resolution of schisis. A 10-month-old boy with congenital retinoschisis developed combined rhegmatogenous and tractional retinal detachment treated by scleral buckle in the right eye and vitreous hemorrhage treated by vitrectomy in the left eye. Combined rhegmatogenous and tractional retinal detachment of the left eye was then treated by vitrectomy with silicone oil.