Ischiofemoral impingement syndrome (IFIS), an unusual presentation of hip pain, is frequently missed in clinical practice. We report a case of a 27-year-old man with complaints of gradual onset nonprogressive right gluteal pain with hip movement restriction for the past 5 years that was not relieved with conservative measures. Right hip magnetic resonance imaging revealed a vascular abnormality of the right quadratus femoris muscle suggestive of IFIS. This abnormal muscle was surgically excised, and its histologic evaluation was remarkable for an arteriovenous malformation.
The patient's longstanding symptomatic IFIS was ultimately attributed to a rare arteriovenous malformation of the quadratus femoris that resolved with surgical excision.